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Case Report
Syngnathia of the anterior mandible in a newborn: Case report
1 DDS, MD, Oral and Maxillofacial Surgeon, Private Practice, Santa Barbara Facial Reconstruction, Santa Barbara, CA, United States
2 DDS, MS, FACS, Cleft and Craniofacial Oral Surgeon, Carolinas Center for Oral and Facial Surgery, Department of Craniomaxillofacial Surgery, Novant Health Presbyterian Medical Center, Charlotte, NC, United States
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Matthew Dailey
334 S. Patterson Ave, Suite 205, Santa Barbara 93111, CA,
USA
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Article ID: 100131Z06MD2025
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How to cite this article
Dailey M, Kapitan R. Syngnathia of the anterior mandible in a newborn: Case report. Case Rep Int 2025;14(1):6–9.ABSTRACT
Introduction: Congenital maxillomandibular fusion is a rare disorder of the craniomaxillofacial skeleton and soft tissue that may present as fusion of the soft tissue, also known as synechiae, or as bony fusion, also known as syngnathia. True maxillomandibular fusion without the involvement of other craniomaxillofacial structures is an uncommon condition with few occurrences documented.
Case Report: We present the case of a newborn infant with intra-utero documented absence of the second through fourth digits on the right hand and micrognathia visualized on ultrasound. No specific syngnathia or cleft lip or palate was noted. At birth he had congenital malformations of the craniomaxillofacial skeleton that included anterior maxillomandibular syngnathia and fusion of a rudimentary tongue with the soft palate.
Conclusion: This case report documents the intra-utero and pre-natal workup, perioperative management, surgical intervention, and postoperative follow-up course for an infant with documented maxillomandibular fusion.
Keywords: Craniofacial, Pediatrics, Synechiae, Syngnathia
SUPPORTING INFORMATION
Author Contributions
Matthew Dailey - Substantial contributions to conception and design, Acquisition of data, Analysis of data, Drafting the article, Final approval of the version to be published
Rick Kapitan - Substantial contributions to conception and design, Acquisition of data, Revising it critically for important intellectual content, Final approval of the version to be published
Guaranter of SubmissionThe corresponding author is the guarantor of submission.
Source of SupportNone
Consent StatementWritten informed consent was obtained from the patient for publication of this article.
Data AvailabilityAll relevant data are within the paper and its Supporting Information files.
Conflict of InterestAuthors declare no conflict of interest.
Copyright© 2025 Matthew Dailey et al. This article is distributed under the terms of Creative Commons Attribution License which permits unrestricted use, distribution and reproduction in any medium provided the original author(s) and original publisher are properly credited. Please see the copyright policy on the journal website for more information.
